Skip to main content
U.S. Department of Energy
Office of Scientific and Technical Information

Human subject with a new defect in repair of ultraviolet damage. [Ultraviolet radiation]

Journal Article · · J. Invest. Dermatol.; (United States)
The subject under study (11961) is a child with extreme sun sensitivity. Fibroblasts derived from the child's skin, like those from patients with the disorder xeroderma pigmentosum were hypersensitive to the lethal effects of 254 nm and 310 nm uv-irradiation. Unlike xeroderma pigmentosum cells, however, fibroblasts from our subject were not hypersensitive to the chemical mutagen N-hydroxyacetylaminofluorene but they were hypersensitive to ethylmethanesulfonate. Furthermore, despite the ultraviolet light sensitivity, no defects could be detected either in excision or postreplication repair of damaged DNA after uv-irradiation of 11961 cells. This again contrasts with xeroderma pigmentosum cells, which are defective in one or the other of these repair processes. On the basis of these characteristics and the clinical symptoms, we are not at present able to classify this patient as having any of the known sun-sensitive syndromes.
Research Organization:
Univ. of Sussex, Brighton, England
OSTI ID:
5760126
Journal Information:
J. Invest. Dermatol.; (United States), Journal Name: J. Invest. Dermatol.; (United States) Vol. 70:4; ISSN JIDEA
Country of Publication:
United States
Language:
English