Skip to main content
U.S. Department of Energy
Office of Scientific and Technical Information

Gene mapping of Usher syndrome type IIa: Localization of the gene to a 2.1-cM segment on chromosome 1q41

Journal Article · · American Journal of Human Genetics
OSTI ID:70386
; ; ;  [1];  [2];  [3]; ;  [4]; ;  [5]
  1. Center for Hereditary Communication Disorders, Omaha, NE (United States)
  2. Univ. of Nebraska, Omaha, NE (United States)
  3. Univ. of Linkoeping Medical School (Sweden)
  4. University Hospital, Nijmegen (Netherlands)
  5. and others

Usher syndrome type II is associated with hearing loss and retinitis pigmentosa but not with any vestibular problems. It is known to be genetically heterogeneous, and one locus (termed USH2A) has been linked to chromosome 1q41. In an effort to refine the localization of USH2A, the genetic map of the region between and adjacent to the marker loci previously recognized as flanking USH2A (D1S70 and PPOL) is updated. Analysis of marker data on 68 Usher II families places the USH2A gene into a 2.1-cM region between the markers D1S237 and D1S229. The gene for transforming growth factor {beta}2 (TGFB2) and the gene for the homeodomain box (HLX1) are both eliminated as candidates for USH2A, by virtue of their localization outside these flanking markers. The earlier finding of genetic heterogeneity was confirmed in six new families, and the proportion of unlinked Usher II families is estimated at 12.5%. The placement of the USH2A gene into this region will aid in the physical mapping and isolation of the gene itself. 30 refs., 4 figs., 2 tabs.

OSTI ID:
70386
Journal Information:
American Journal of Human Genetics, Journal Name: American Journal of Human Genetics Journal Issue: 1 Vol. 56; ISSN AJHGAG; ISSN 0002-9297
Country of Publication:
United States
Language:
English

Similar Records

Construction of a YAC contig and STS map spanning at least 10 cM in 1q41, the critical region of Usher II gene
Journal Article · Thu Sep 01 00:00:00 EDT 1994 · American Journal of Human Genetics · OSTI ID:134490

The construction of a yeast artificial chromosome (YAC) contig in the vicinity of the Usher syndrome type IIa (USH2A) gene in 1q41
Journal Article · Mon Jul 01 00:00:00 EDT 1996 · Genomics · OSTI ID:466021

Genetic heterogeneity of usher syndrome type 1 in French families
Journal Article · Sun May 01 00:00:00 EDT 1994 · Genomics; (United States) · OSTI ID:7029724