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The Marinesco-Sjoegren syndrome examined by computed tomography, magnetic resonance, and sup 18 F-2-fluoro-2-deoxy-D-glucose and positron emission tomography

Journal Article · · Archives of Neurology; (USA)

The Marinesco-Sjoegren syndrome is an autosomal recessive degenerative disorder characterized by congenital cataracts, cerebellar ataxia, spasticity, mental deficiency, and skeletal abnormalities. We studied two adult siblings with Marinesco-Sjoegren syndrome using anatomic and metabolic brain imaging techniques to characterize the pattern and nature of abnormalities in the brain. Computed tomographic and magnetic resonance imaging showed diffuse brain atrophy of mild to moderate degree, involving primarily the white matter of the cerebrum, cerebellum, brain stem, and cervical spinal cord. The pattern of atrophy resembled that seen in diffuse leukoencephalopathies. Measurements of local cerebral glucose metabolic rates with positron emission tomography revealed no statistically significant differences from normal control subjects in most regions, but metabolic rate was decreased in the thalamus in one patient. The findings support a diffuse white matter disorder in Marinesco-Sjoegren syndrome.Aut

OSTI ID:
6070595
Journal Information:
Archives of Neurology; (USA), Journal Name: Archives of Neurology; (USA) Vol. 47:11; ISSN 0003-9942; ISSN ARNEA
Country of Publication:
United States
Language:
English