skip to main content
OSTI.GOV title logo U.S. Department of Energy
Office of Scientific and Technical Information

Title: Molecular pathology and haplotype analysis of Wilson disease in Mediterranean populations

Journal Article · · American Journal of Human Genetics
OSTI ID:186201
; ;  [1]
  1. Universita degli Studi di Cagliari (Italy); and others

We analyzed mutations and defined the chromosomal haplotype in 127 patients of Mediterranean descent who were affected in Wilson disease (WD): 39 Sardinians, 49 Italians, 33 Turks, and 6 Albanians. Haplotypes were derived by use of the microsatellite markers D13S301, D13S296, D13S297, and D13S298, which are linked to the WD locus. There were five common haplotypes in Sardinians, three in Italians, and two in Turks, which accounted for 85%, 32%, and 30% of the WD chromosomes, respectively. We identified 16 novel mutations: 8 frameshifts, 7 missense mutations, and 1 splicing defect. In addition, we detected the previously described mutations: 2302insC, 3404delC, Arg1320ter, Gly944Ser, and His1070Gin. Of the new mutations detected, two, the 1515insT on haplotype I and 2464delC on haplotype XVI, accounted for 6% and 13%, respectively, of the mutations in WD chromsomes in the Sardinian populations. Mutations H1070Q, 2302insC, and 2533delA represented 13%, 8%, and 8%, respectively, of the mutations in WD chromsomes in other Mediterranean populations. The remaining mutations were rare and limited to one or two patients from different populations. Thus, WD results from some frequent mutations and many rare defects. 28 refs., 1 fig., 3 tabs.

OSTI ID:
186201
Journal Information:
American Journal of Human Genetics, Vol. 57, Issue 6; Other Information: PBD: Dec 1995
Country of Publication:
United States
Language:
English

Similar Records

The Wilson disease gene: Haplotypes and mutations
Journal Article · Thu Sep 01 00:00:00 EDT 1994 · American Journal of Human Genetics · OSTI ID:186201

Spectrum of mutations in the major human skeletal muscle chloride channel gene (CLCN1) leading to myotonia
Journal Article · Fri Dec 01 00:00:00 EST 1995 · American Journal of Human Genetics · OSTI ID:186201

Molecular characterization of beta-thalassemia in the Sardinian population
Journal Article · Sat Feb 01 00:00:00 EST 1992 · American Journal of Human Genetics; (United States) · OSTI ID:186201